Congenital Solitary Angiokeratoma of Tongue: A Rare Case Report

Manupriya Nain, Shilpi Agarwal, Gautam bir Singh, Raghuram Devenga

Abstract


Angiokeratoma is a rare cutaneous vascular disorder that can occur in several clinically distinct conditions. Oral mucosal angiokeratomas are rare and commonly seen as a component of angiokeratoma corporis diffusum. An 11 year old female child presented with swelling on dorsal surface of tongue since birth. Swelling was erythematous, sessile, non tender. There were no other lesions on oral mucosa or anywhere on skin. Surgical excision was done and on histopathological analysis a diagnosis of angiokeratoma was made. Isolated oral Angiokeratomas are rare. Previous literature search revealed only a single case of Angiokeratoma of tongue with congenital etiology. We are describing a case of angiokeratoma of tongue which is solitary and congenital.


References


Mibelli V. Di una nuova forma di cheratosis, angiocheratoma. G Ital Mal Vener 1889;30:285-301.

Fordyce JA. Angiokeratoma of the scrotum. J Cutan Genitourin Dis 1896;14:81-7.

Fabry J. Uber einen Fall von angiokeratoma circumscriptum am linken Oberschenkel. Dermatol Zeitschr 1915;22:I-4.

Imperial R, Helwig EB. Angiokeratoma. A clinicopathological study. Arch Dermatol 1967;95:166-75.

Imperial R, Helwig EB. Angiokeratoma of the vulva. Obstet Gynecol 1967;29:307-12.

Ranjan N, Mahajan KV. Oral angiokeratomas: Proposed clinical classification. Int J Dermat 2009;48:778-81.

Karthikeyan K, Sethuraman G, Thappa DM. Angiokeratoma of the oral cavity and scrotum. J Dermatol 2000;27:131-2.

Miller DA, Akers WA. Multiple Phlebectasia of the jejunum, oral cavity and scrotum. Arch Intern Med 1968;121:180-2.

Yildrim M, Kilinc N, Oktay MF, Topcu I. A case of solitary angiokeratoma circumscriptum of the tongue. Kulak Burun Bogaz Ihtis Derg 2007;17:333-5.

Leung CS, Jordan RC. Solitary angiokeratoma of the oral cavity. Oral Surg Oral Med Oral Pathol Oral Radiol Endod 1997;84:51-3.

Kumar MV, Thappa DM, Shanmugam S, Ratnakar C. Angiokeratoma circumscriptum of the oral cavity. Acta Derm Venereol 1998;78:472.

Bhargava P, Bhargava S, Mathur D, Agarwal US, Bhargava R. Angiokeratoma of tongue . Indian J Dermatol Venereol Leprol 2001;67:270.

Vijaykumar M, Thappa DM, Kathikeyan K, Jayanthi S. Angiokeratoma cirumscriptum of the tongue. Pediatr Dermatol 2003;20:180-2.

Varshney S. Angiokeratoma circumscriptum of the tongue. Int J Dermatol 2005;44:886-8.

Siponen M, Penna T, Apaja Sarkkinen M, Palatsi R, Salo T. Solitary angiokeratoma of the tongue. J Oral Pathol Med 2006;35:252-3.

Ergun S, Mete O, Yesil S, Tanyeri H. Solitary angiokeratoma of the tongue treated with diode laser. Lasers Med Sci 2007;24(1):123-5. DOI: 10.1007/s10103-007-0525-z

Sion-Vardy N, Manon E, Puterman M, Bodner L. Solitary angiokeratoma of the tongue. Med Oral Pathol Oral Cir Bucal 2008;13:E12-4.

Schiller PI, Itin PH. Angiokeratomas: an update. Dermatology. 1996;193(4):275-82.

Segura-Saint Gerouns R, Toro-Tojas M, Ceballos-Salobrena A, Aparicio- Soria JL, Fuentes -Vaamonde H. Focal epithelial hyperplasia A rare disease in our area. Med Oral Pathol Oral Cir Bucal 2005;10(2):128-31.

Green J, Roy S. Angiokeratoma circumscriptum of dorsal tongue in a child. Int J Pediatric Otorhinolaryngology 2006;1:107-9.


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